<b><br>Introduction:</b> The different theories concerning the perinatal sternocleidomastoideus muscle problems are discussed in numerous reviews. Perinatal injuries of mentioned muscle have been the subject of controversy since they were first postulated by Stromeyer in 1838. Sternocleidomastoideus characterized by fibrosis, result in a shortening and consequent limited neck motion. When left untreated, may result in progressive limitation of head movement which may cause eye movement disorder, craniofacial asymmetry, neck pain and compensatory asymmetrical spine curvature that worsens with age.</br> <b><br>Aim:</b> This research presents a very rare case of perinatal sternocleidomastoideus muscle injury with gentle torticollis and neck swelling in a 4-week-old girl treated with manual therapy.</br> <b><br>Case report:</b> The patient with normal spontaneous vaginal delivery. Born at 38 weeks gestational age with 3710 g weight, 58 cm of birth height, scored at 10 APGAR. Head tilt was observed since birth and the lump occurred at 1 week after. USG examination showed a lesion 33.6 x 14.9 mm of the SCM. The baby underwent three manual treatment units, a one week apart.</br> <b><br>Results:</b> Resolve of swelling and restore a full passive and active range of motion in the cervical spine was achieved after the treatment. USG examination reveal image corresponded to reorganization and healing of muscle fibers.</br> <b><br>Conclusions:</b> Manual therapy with proper care can be an effective strategy of perinatal SCM injury treatment.</br>