The focus of the present letter to editor is on keloid formation and its management following treatment of congenital form of Boutonniere finger. Keloids and hypertrophic scars represent fibroblast-mediated hyperactive response to dermal injuries that extend beyond the wound margins, causing functional and aesthetic impairments.[1] Keloids most commonly develop on chest, ear lobe, shoulders, and upper arm.[2] [3] Lesions which extend beyond the wound borders are called keloids.[4] They usually appear in areas such as ear, chest, and deltoid regions.[2] They are usually the result of fibroblast abnormal proliferation and accumulation of excessive extracellular matrix during wound healing.[3] Herein, we describe an atypical keloid on the finger of a 3-year old patient after treatment of congenital deformity.