In our study, we present a case that developed orbital apex syndrome after strabismus surgery. Nineteen years old female patient referred to our clinic with a decrease of vision, ptosis, limitation of eye movements and pain on left eye that began 5 days ago. There was a strabismus surgery history about 4 months ago on left eye. With ophthalmologic examination, best corrected visual acuity was 10/10, intraocular pressure was 15 mmHg, eyelids, eye movements, anterior segment and fundus was normal on the right eye. On the left eye, best corrected visual acuity was 5/10, intraocular pressure was 23 mmHg. There was ptosis that close approximately 2/3 of pupil field. At the evaluation of extraocular muscle movements, there was limitation while looking up, down, in, and out. At the examination of the anterior segment, pupil was dilated; there was no direct and indirect light reflex. Fundus examination of left eye was normal. With remaining findings, we diagnosed the object as orbital apex syndrome and planned the treatment. Orbital apex syndrome after strabismus surgery has not been described yet. For this reason, this case report has been found worth to present.