Lingual Osseous Choristoma: A Case Report and Review of the Literature

Mine Ozsen,Selin Narter,Ozlem Saraydaroglu

doi:10.31557/apjcc.2019.4.4.145-149

Abstract

Introductıon: Osseous choristoma is a benign lesion that is characterized by proliferation of mature osseous tissue in an abnormal anatomical location. The lesion, which was first described by Monserrat in 1913 as “lingual osteoma” has been called “osseous choristoma” since 1971. Here, we present a rare case of osseous choristoma located on the tongue and a review of the literature.Case Report: A 26 year-old male patient was referred to the Department of ENT with the complaint of swelling of the tongue. Physical examination showed a nodular, sessile lesion on the base of the tongue and the lesion was removed. Histopathological examination of the material revealed a well-defined, submucosal lesion consisting of mature bone tissue and was reported as “osseous choristoma”.Conclusıon: Osseous choristoma is a benign lesion that occurs mostly in women in their second or third decades of life, although it can be seen in a wide age range. Osseous choristoma may occur in different locations of the oral cavity and maxillofacial region such as the tongue, buccal mucosa, alveolar mucosa, submandibular region, submental region, masseter muscle and palate. This rare entity should be kept in mind because it may be confused with other benign lesions of the tongue like hemangioma, lymphangioma, hamartoma and malignant tumors.

Highlights

Choristoma is defined as the proliferation of normal tissue in an abnormal anatomical location
Osseous choristoma is a benign lesion that develops with the proliferation of mature bone tissue in an abnormal region in which bone tissue is not normally found
Discussion and Review of the Literature We searched the literature in PUBMED, MEDLINE, Google Scholar and XXXXX Library database using the keywords “lingual”, “osseous”, “choristoma”, “tongue”, “lesion” and their combinations

Summary

Introduction

Choristoma is defined as the proliferation of normal tissue in an abnormal anatomical location. Choristomas located in the oral cavity may consist of various tissues such as bone, cartilage, glial tissue, gastric mucosa and sebaceous glands [1]. Osseous choristoma is a benign lesion that develops with the proliferation of mature bone tissue in an abnormal region in which bone tissue is not normally found. This entity was first defined in 1913 by Monserrat as “lingual osteoma”. Histopathological examination revealed a submucosal, well-demarcated nodular lesion consisting of osseous tissue beneath non-keratinizing squamous epithelium (Figure 1). The bone tissue showed lamellation with well-developed Haversian system. Osteoblastic, osteoclastic activity, mitosis or cytological atypia was not seen (Figure 2)

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Discussion