Endobronchial sialolipoma. Case report

Severino Rey Nodar,Hugo D Boccara,Verónica García Yllán,Onay Solis,Nohelia Rojas Ferrer

doi:10.1186/s13000-021-01074-7

Severino Rey Nodar, Hugo D Boccara + Show 3 more

Open Access

https://doi.org/10.1186/s13000-021-01074-7

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Abstract

BackgroundA 52-year-old woman presented with shortness of breath and cough. An endobronchial sialolipoma was found at the left entrance of the main bronchus. Sialolipoma is an exceedingly rare type of lipoma reported of the minor salivary glands, especially within the bronchus.Case presentationA 52-year-old woman presented with shortness of breath and cough with 6 months´ evolution. Endobronchial endoscopy revealed a tumour at the left entrance of the main bronchus. The entire removal of the tumour was removed using a cryoprobe device. Pathological examination showed a tumour consistent with the diagnosis of sialolipoma due to the presence of mature adipose cells blended with acinar, ductal, basal, and myoepithelial cells. The patient had a favourable outcome.ConclusionThe infrequent tracheobronchial presentation of this tumour can be challenging for correct diagnosis.

Highlights

A 52-year-old woman presented with shortness of breath and cough
Lipomas are common benign mesenchymal tumours originated in the human body [1, 2], and Sialolipoma is a remarkably rare type of lipoma found in the major and minor salivary glands that consisting of mature adipocytes intermingled with glandular tissue [3]
Nagao T et al [3], proposed the designation of sialolipoma to characterize this new category of a benign lipomatous tumour occurring in the salivary glands or in any oral or maxillofacial site, consisting of islands of epithelial salivary gland elements enclosed in mature adipose tissue and bounded by a thin fibrous tissue

Summary

Background

Tracheobronchial tree obstructions can be caused by endobronchial tumours despite their clinical and biological behaviour. Nagao T et al [3], proposed the designation of sialolipoma to characterize this new category of a benign lipomatous tumour occurring in the salivary glands (mainly in the parotid gland) or in any oral or maxillofacial site, consisting of islands of epithelial salivary gland elements (acinar and ductal structures) enclosed in mature adipose tissue and bounded by a thin fibrous tissue. This tumour typically occurs in adults (90%), with fewer cases reported in infants [3, 4]. Gross examination showed a round shape, smooth surface, solid and whitish-pink tumour histologically consistent with a sialolipoma due to the presence of mature adipose cells blended with acinar, ductal, basal, and myoepithelial cells (Figs. 2, 3, 4 and 5)

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Discussion and conclusions

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