Congenital cystic adenomatoid malformation of the lung in adults: report of two cases and review of the literature.

Abstract

Congenital cystic adenomatoid malformation (CCAM) is characterized by adenomatoid proliferation of bronchiole-like structures and cysts formation. It isan uncommon cause of respiratory distress in infants. Most common presentation is in first two years of life with complaints of respiratory distress.Presentation in adulthood is rare. Surgical intervention is the mainstay treatment.We describe two cases of atypical CCAM presenting in adulthood with past history of tuberculosis. To our knowledge only one case of CCAM with tuberculosis has been reported in literature.