Bilateral scrotoshisis a rare entity: case report

Shazia Perveen,Sajid Ali,Mishraz Shaikh

doi:10.1186/s43159-020-00067-3

Shazia Perveen, Sajid Ali + Show 1 more

Open Access

https://doi.org/10.1186/s43159-020-00067-3

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Abstract

BackgroundScrotoschisis is a rare anomaly in which the testis is lying outside scrotum congenitally. Only few cases have been reported in literature under different names most of which are unilateral. We have found only one case of bilateral scrotoschisis in literature.Case presentationNewborn presented to us after normal term twin delivery as a case of bilateral scrotoschisis in which both testes were lying outside the scrotum congenitally. Baby underwent uneventful bilateral orchiopexy and was discharged home the next day.ConclusionScrotoschisis is a very rare genital anomaly with only a few cases reported in literature. This report would add to the literature which would help in studying the exact mechanism and embryopathogenesis of this anomaly which is not known yet.

Highlights

Scrotoschisis is a rare anomaly in which the testis is lying outside scrotum congenitally
Genital examination showed normal penis with normal urethral opening, bilaterally scrotum was well developed, with rugosities and pigmentation. Both testes were exposed and hanging outside vertically through two transverse anterior scrotal wall defects on both sides of median raphe, with healthy edges; both testes were pink and healthy but edematous due to prolonged exposure; midline raphe was intact with separate spacious testicular compartments
Testicular fixation was done with interrupted sutures to prevent torsion of the testes, midline raphe was reconstructed by anchoring the midline prominent tissue to anterior wall, and scrotal skin was closed with absorbable vicryl mattress sutures

Summary

Introduction

Scrotoschisis is a rare anomaly in which the testis is lying outside scrotum congenitally. Background Scrotoschisis is an extremely rare condition that present congenitally in which one or both testes are lying outside the scrotum through a scrotal wall defect. To the best of our knowledge, only one case of bilateral scrotoschisis has been reported till date [5].

Results

Conclusion