A rare case of pseudoaneurysm at the site of untreated coarctation of the aorta in an adult patient

Takuma Mikami,Yosuke Kuroda,Hiroki Uchiyama,Ryo Harada,Takeshi Kamada,Syuichi Naraoka,Nobuyoshi Kawaharada

doi:10.1007/s11748-020-01525-w

Takuma Mikami, Yosuke Kuroda + Show 5 more

Open Access

https://doi.org/10.1007/s11748-020-01525-w

Copy DOI

Abstract

Here we report a rare case of pseudoaneurysm at the site of aortic coarctation. Aortic coarctation and a saccular aortic aneurysm protruding from the site of this coarctation were detected in a 50-year-old woman. Owing to the shape of the aneurysm and high risk of rupture, an open surgical repair was performed. The pathological findings of the removed aneurysm revealed a pseudoaneurysm consisting of only a thin adventitial wall. Adult uncorrected aortic coarctation has a poor prognosis. One of its causes may be the formation of such a pseudoaneurysm.

Highlights

We present a rare case of a patient with CaseCoarctation of the aorta (CoA) who was asymptomatic until the age of 50 and had a pseudoaneurysm protruding from the site of aortic coarctation
It is thought that the pseudoaneurysm rupture as in this case may be one of the causes of the poor prognosis of adult aortic coarctation
A computed tomography scan (CT) showed CoA and a saccular aortic aneurysm protruding from the aortic coarctation

Summary

Introduction

Coarctation of the aorta (CoA) has been reported to account for 4–8% of congenital heart diseases [1,2,3]. We present a rare case of a patient with CoA who was asymptomatic until the age of 50 and had a pseudoaneurysm protruding from the site of aortic coarctation. A computed tomography scan (CT) showed CoA and a saccular aortic aneurysm protruding from the aortic coarctation. A saccular aneurysm protruding dorsally from the coarctation was observed (Fig. 1a, b). Anastomosis was performed by clamping the central side of the descending thoracic aorta at the Th8 level without deep hypothermic circulatory arrest. A postoperatively contrast-enhanced CT scan revealed a complete coarctation resection, and no abnormal findings were observed in the artificial blood vessel anastomosis (Fig. 1d).

Discussion

Findings

Compliance with ethical standards