SESSION TITLE: Medical Student/Resident Cardiothoracic Surgery Posters SESSION TYPE: Med Student/Res Case Rep Postr PRESENTED ON: October 18-21, 2020 INTRODUCTION: Bronchogenic cysts (BCs) are singular congenital variances that surface early from anomalous budding of the maturing respiratory system between the 26th and 40th day of gestation (1). Most BCs are asymptomatic until they compress the surrounding structures. BCs are commonly seen in the mediastinum or intrapulmonary; with a previously reported prevalence of 1 per 42,000 and 1 per 68,000 admissions. They account for 50% to 60% of all mediastinal cysts. If incomplete resected, there is very high recurrence rate (2). We report a patient with second recurrence of mediastinal BC noted 18 years after initial drainage without resection. CASE PRESENTATION: A 57-year-old female with history of biopsy-proven BC with mediastinoscopy drainage followed by first recurrence treated with thoracoscopic drainage. Symptoms at presentation included three days of chest pain radiating between the scapula, associated with shortness of breath, low grade fever, and a dry cough. Vital signs were stable and lab-work was remarkable for WBC of 15.03 K/mm3 with 1% immature granulocytes. Chest x-ray showed a right paratracheal soft tissue density measuring 4.5 cm. Chest CT showed a large low-attenuation mass measuring 8 x 4.8 cm in the mediastinum region with 23 Hounsfield unit density (Image 1,2). Patient underwent video-assisted thoracoscopy converted to right thoracotomy for incision and drainage with sclerotherapy of the BC. Biopsy showed benign fibrous tissue with respiratory epithelium consistent with BC without atypia (Image 3). No growth was appreciated on stain and culture. Serial chest x-rays prior to discharge showed resolution of the soft tissue density. Improvement of respiratory symptoms upon surgery and treatment of community-acquired pneumonia with Rocephin 1gm IV QD and Azithromycin 500mg IV QD for five days. DISCUSSION: With the help of this case report we hope to shed light on the fact that symptomatic cysts should be resected either by thoracotomy or via video-assisted thoracoscopy (VAT) regardless of patient age, unless surgical risks are unacceptably high, as in our patient due to proximity of prominent vessels (3). Although many asymptomatic cases have been reported, a number of complications with BCs have been described, with infection being the most common followed by respiratory obstruction. While there has been a recent rise in the use of thoracoscopic techniques for resection of bronchogenic cysts in adults, one should not forget about patients with high surgical risks. The benefits of thoracoscopy drainage are decreased scarring, reduced pain, and shorter hospitalization (4). CONCLUSIONS: If incomplete resection or drainage is done, as seen in this patient, then residual mucosa should be treated by toxic agents or electrocautery (5). We propose serial imaging to monitor for recurrence when incomplete resection or drainage is done, as no current guidelines are present. Reference #1: 1) Reichelt O, Grieser T, Wunderlich H, Möller A, Schubert J. Bronchogenic cyst. A rare differential diagnosis of retroperitoneal tumors. Urol Int. 2000;64(4):216-219. Reference #2: 2) Limaïem F, Ayadi-Kaddour A, Djilani H, Kilani T, El Mezni F. Pulmonary and mediastinal bronchogenic cysts: a clinicopathologic study of 33 cases. Lung. 2008;186(1):55-61. Reference #3: 3) McAdams HP, Kirejczyk WM, Rosado-de-Christenson ML, Matsumoto S. Bronchogenic cyst: imaging features with clinical and histopathologic correlation. Radiology. 2000;217(2):441-446. 4) Lee DH, Park CK, Kum DY, Kim JB, Hwang I. Clinical characteristics and management of intrathoracic bronchogenic cysts: a single center experience. Korean J Thorac Cardiovasc Surg. 2011;44(4):279-284. [5] Rice DC, Putnam JB. Recurrent bronchogenic cyst causing recurrent laryngeal nerve palsy. Eur J Cardiothorac Surg 2002;21:561–3. DISCLOSURES: No relevant relationships by Loui Abdelghani, source=Web Response No relevant relationships by Hesham Afify, source=Web Response No relevant relationships by George Alvarez, source=Web Response No relevant relationships by Manuel Carrazana, source=Web Response No relevant relationships by Maria Wallis-Crespo, source=Web Response
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