ABSTRACTWhenever there is pneumatization of either turbinate, it is known as concha bullosa (CB). In the case of middle turbinate, it is the most common anatomical aberration. A mucopyocele of CB is very rarely seen. A 13-year-old male presented with the complaints of gradually progressive swelling on medial aspect of right eye with nasal obstruction, nasal discharge, and facial heaviness for 3 years. Computed tomography (CT) scan of the paranasal sinuses showed a well-defined cystic lesion of thick fluid attenuation with thin shell in the periphery located at the medial canthus of right eye involving the lacrimal sac region with stranding of adjacent periorbital fat plane. Lesion is seen causing erosion of lamina papyracea. After complete hematological and preanesthetic assessment, surgery was planned for the patient under general anesthesia. The lateral lamella and inferior part of CB was excised to drain out the pus and prevent recurrences. Patient remained symptom free in the follow-up period.How to cite this articleSingh HP, Kumar S, Hajela A, Agarwal SP. Mucopyocele of Concha Bullosa: A Rare Presentation as Orbital Swelling. Int J Otorhinolaryngol Clin 2016;8(2):53-55.